Oral Presentation 1st Asia Pacific Herbert Fleisch Workshop 2025

LepR + MMP9 + stromal progenitor cells orchestrate trabecular bone growth and metabolism (#29)

Karishma Desai 1 , Shinichirou Ito 2 , Tomoaki Iwayama 3 , Yoshiaki Kanemoto 4 5 , Takahiro Sawada 4 5 , Shigeaki Kato 4 5 , Takashi Nakamura 1 , Yasuhiro Kobayashi 6 , Nobuyuki Udagawa 7 , Masataka Kasahara 2 , Toshihide Mizoguchi 1
  1. Oral health science centre, Tokyo Dental College, Chiyoda-ku, Tokyo, Japan
  2. Department of Pharmacology, Tokyo Dental College, Chiyoda-ku, Tokyo, Japan
  3. Department of Periodontology and Regenerative Dentistry, Osaka University Graduate School of Dentistry, Suita, Osaka 565-0871, Japan
  4. Graduate School of Life Science and Technology, Iryo Sosei University, Iwaki-shi, Fukushima 970-8551, Japan
  5. Research Institute of Innovative Medicine, Tokiwa Foundation, Iwaki-shi, Fukushima 972-8322, Japan
  6. Division of Hard Tissue Research, Institute for Oral Science, Matsumoto Dental University, Shiojiri, Nagano 399-0781, Japan
  7. Department of Oral Biochemistry, Matsumoto Dental University, Shiojiri, Nagano 399-0781, Japan

Objective: Skeletal stromal progenitor cells in the metaphysis (met-SSPCs) contribute to trabecular bone (Tb) formation by supplying osteoblast lineages during postnatal (PN) growth.1,2 Although metaphyseal precursors derived from the hypertrophic chondrocyte or Sox-9 lineage are essential for Tb formation2, the underlying mechanism regulating Tb homeostasis remains unclear. Using inducible Cre-LoxP system, we aimed to identify the metaphyseal SSC population and their functional characteristics during bone growth and metabolism.

Methods and Results: Lineage tracing and Single-cell RNA-seq analysis of mice at PN day 28 showed that met-SSPCs originate from Asporin+ periosteal cells. Genetic ablation of the met-SSPCs lineage impairs Tb formation, reduces cross-sectional area, and shortens bone length. Largely, the met-SSPC subpopulation expressing Leptin receptor (LepR+) and matrix metalloproteinase (MMP9+) contributed to bone growth via differentiation into osteoblasts and LepR+/CXCL12-abundant reticular (CAR) cells. Their lineage expansion correlates with increased bone turnover and stemness gene expression. Notably, osteoclast differentiation factors RANKL and M-CSF, were highly expressed in LepR+MMP9+ and LepR+/CAR cells than in osteoblasts and osteocytes. Micro-CT examination revealed that conditional deletion of Rankl in LepR+ cells, but not in osteoblast-lineage cells, increased the Tb mass. Tartrate-resistant acid phosphatase staining of LepR-CreER mice femur was in congruence with the micro-CT data, thus indicating that LepR+ derived RANKL is essential for osteoclast activation and function.

Conclusion: These findings suggest that a novel functional subset of LepR⁺ progenitors is essential for Tb growth and homeostasis. We put forth that the LepR+MMP9+ progenitors are vital for both osteogenesis and osteoclast activation.

  1. Shi, Y.; He, G.; Lee, W.C.; McKenzie, J.A.; Silva, M.J.; and Long, F. Nat Commun, 2017, 8, 2043.
  2. Ono, N.; Ono, W.; Nagasawa, T.; and Kronenberg, H.M. Nat Cell Biol, 2014, 16, 1157-1167